Isolation of cDNA coding for an ubiquitous membrane protein deficient in high Na+, low K+ stomatocytic erythrocytes

Article


Stewart, G., Hepworth-Jones, B., Keen, J., Dash, B., Argent, A. and Casimir, C. 1992. Isolation of cDNA coding for an ubiquitous membrane protein deficient in high Na+, low K+ stomatocytic erythrocytes. Blood. 79 (6), pp. 1593-1601.
TypeArticle
TitleIsolation of cDNA coding for an ubiquitous membrane protein deficient in high Na+, low K+ stomatocytic erythrocytes
AuthorsStewart, G., Hepworth-Jones, B., Keen, J., Dash, B., Argent, A. and Casimir, C.
Abstract

Human red blood cells (RBCs) that are deficient in an integral membrane-associated protein ("stomatin") of apparent molecular mass 31 Kd show a catastrophic increase in passive membrane permeability to the univalent cations Na+ and K+ and are stomatocytic in shape. We have purified this protein from normal RBC membranes and isolated a cDNA clone coding for it. The deduced protein sequence is unrelated to that of any known ion-transport-related protein. Selective solubilization studies using detergents show that while the protein is strongly associated with the phospholipid bilayer, it also binds to the cytoskeleton. The predicted polypeptide has a single trans-membranous hydrophobic segment near the N-terminus, which would locate it in the membrane; the large C-terminal domain is hydrophilic and cytoplasmic in orientation and is presumed to be responsible for the attachment to the cytoskeleton. By inference, the protein has the function of closing a latent ion channel. The messenger RNA encoding this protein is ubiquitously distributed in different human cell types and tissues and is thus presumably a widely distributed regulator of transmembrane cation fluxes. As a membrane-bound inhibitor protein of Na+ and K+ transport, it is unique among the known components of membrane-transport proteins.

Research GroupMolecular Biology group
PublisherAmerican Society of Hematology
JournalBlood
ISSN0006-4971
Publication dates
Print1992
Publication process dates
Deposited02 Dec 2009
Output statusPublished
Web address (URL)http://bloodjournal.hematologylibrary.org/cgi/content/short/79/6/1593
LanguageEnglish
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